- name
- bio-crispr-screens-base-editing-analysis
- description
- Analyzes base-editing screens for variant function. Covers library design (Hanna 2021 ClinVar-scale CBE screen benchmarked on BRCA1/2, Cuella-Martin 2021 DDR saturation), CBE vs ABE chemistry choice (BE3/BE4 vs ABE7.10/ABE8.20/ABE8e), editing-window math (positions 4-8 from PAM-distal end; 4-7 for ABE7.10), bystander-edit quantification and the variant-call ambiguity it creates, sgRNA-efficiency filtering before hit calling, indel byproduct interpretation, the substitution-vs-indel diagnostic, variant annotation against ClinVar / COSMIC, and the Broad be-validation-pipeline. Use when designing a BE variant screen, choosing CBE vs ABE for a specific edit, interpreting bystander-confounded hits, distinguishing functional signal from indel artifact, integrating CRISPResso2 output with screen scoring, or deciding BE vs PE for SNV installation.
- tool_type
- mixed
- primary_tool
- CRISPResso2
## Version Compatibility
Reference examples tested with: CRISPResso2 2.2.14+, BE-Hive 1.0+ (BE prediction), pandas 2.2+, biopython 1.83+, numpy 1.26+, scipy 1.12+, scikit-learn 1.4+; Broad be-validation-pipeline notebooks (repo HEAD).
Before using code patterns, verify installed versions match. If versions differ:
- CLI: `CRISPResso --version`
- Python: `pip show CRISPResso2`; BE-Hive is a GitHub clone (maxwshen/be_predict_bystander), not a PyPI package
If code throws ImportError, AttributeError, or TypeError, introspect the installed package and adapt the example to match the actual API rather than retrying.
## Base Editing Screen Analysis
**"Analyze my base-editor variant-function screen"** -> Quantify per-sgRNA target-base conversion, bystander rate, and indel byproducts from amplicon sequencing; filter on editing efficiency; map each sgRNA to its intended SNV (target + bystander pattern); compute per-variant fitness from the screen log-fold change; reconcile target vs bystander variant attribution; annotate against ClinVar / COSMIC.
- CLI: `CRISPResso --base_editor_output` for per-amplicon BE quantification
- CLI: Broad `be-validation-pipeline` for end-to-end pooled-screen analysis with editing-efficiency filtering
- Python: `BE-Hive` (Arbab 2020) for editing-efficiency prediction; clone maxwshen/be_predict_bystander and import via sys.path
- Web: `BE-Designer` (Hwang 2018, RGEN Tools) for variant-encoding sgRNA design
## Base Editor Chemistry Selection
| Editor | Reaction | Editing window | Indel byproduct rate | When to use |
|--------|----------|----------------|----------------------|-------------|
| BE3 (Komor 2016) | C->T (also G->A on opposite strand) | Pos 4-8 from PAM-distal end | 5-10% | Original; superseded |
| BE4 / BE4max (Koblan 2018) | C->T | Pos 4-8 | <5% | CBE standard |
| eA3A-BE3 | C->T narrow specificity | Pos 5-7 | <5% | Specifically TC contexts (eA3A prefers TC) |
| ABE7.10 (Gaudelli 2017) | A->G (T->C opposite strand) | Pos 4-7 | <2% | First ABE; slow at non-TA contexts |
| ABE8.20 (Gaudelli 2020) | A->G | Pos 4-8 | <2% | Modern ABE; high activity |
| ABE8e (Richter 2020) | A->G | Pos 4-8 | <2% | Highest editing activity; more processive than ABE7.10 |
| evoCDA-BE | C->T (broader) | Pos 1-9 | 5-10% | Larger editing window; more bystander |
| CGBE1 (Kurt 2021) | C->G | Pos 5-7 | 5-10% | C-to-G transversion; rare use |
| GBE (Zhao 2021) | C->G or C->A | Pos 4-7 | 5-10% | Transversions; less mature |
**Decision rule:** For a target SNV at position 4-8 of a candidate spacer with no bystander Cs/As in the same window, BE3-BE4 or ABE7.10 is sufficient. For high-throughput variant scanning where bystander tolerance must be minimized, use eA3A-BE3 (TC contexts only) for C->T, or ABE7.10 rather than ABE8e/ABE8.20 for A->G -- its 4-7 window is the narrowest ABE.
## Editing Window Math
**Why this matters for postdoc-level use:** Base editors are tethered to dCas9 (or nCas9) and the deaminase acts on the displaced ssDNA "R-loop" formed when Cas9 binds. The deaminase has a fixed reach -- positions 4-8 from the PAM-distal end of the protospacer for canonical BE3/BE4, and 4-7 for ABE7.10. Outside this window, editing efficiency drops by 10-50x.
```
PAM-distal end PAM-proximal
| |
1 2 3 4 5 6 7 8 9 10 11 12 13 14 15 16 17 18 19 20 NGG
^^^^^^^^^^^
Canonical editing window (positions 4-8)
For BE4max: positions 4-8 are 5-50x more efficient than positions 1-3 or 9-13 (ABE7.10: 4-7)
For SpABE8e: positions 4-8 (Richter 2020), matching the corresponding CBEs rather than ABE7.10's narrower 4-7
For evoCDA-BE: window 1-9 (broader; more bystander)
```
**Critical implication for variant interpretation:** If the intended edit is at position 5 and there is an additional editable C/A at position 7, both will be edited in the same molecule. The screen scores the *combination* of edits, not the intended one alone. This is bystander confounding.
## sgRNA Library Design for BE Screens
**Goal:** Tile editing-window-positioned spacers across a protein region of interest to enable variant scanning.
**Approach:** For each amino acid in the target region, find NGG-adjacent spacers where the SNV-of-interest base falls in editing positions 4-8 with minimal bystander C/A in the same window. Annotate each spacer with the predicted amino acid changes (target + bystander).
```python
import pandas as pd
import re
from Bio.Seq import Seq
def find_be_spacers(cds_sequence, cds_protein_start, target_aa, target_base='C', editor='BE4max'):
'''Find sgRNAs that place target_base in editor-specific window at target_aa.
Returns spacers with bystander annotation.
Args:
cds_sequence: nucleotide CDS (translated frame 1)
cds_protein_start: amino acid number of CDS start (usually 1)
target_aa: amino acid number to install variant (e.g., 130 for residue 130)
target_base: 'C' (CBE) or 'A' (ABE)
editor: 'BE3', 'BE4max', 'eA3A-BE3', 'ABE7.10', 'ABE8.20', 'ABE8e', 'evoCDA-BE'
Returns: DataFrame with spacer, position-in-cds, target-base-position-in-spacer,
bystander_positions, predicted_aa_changes
'''
# Editor-specific editing window (positions from PAM-distal end of spacer)
window_by_editor = {
'BE3': (4, 8), 'BE4max': (4, 8), 'eA3A-BE3': (5, 7),
'ABE7.10': (4, 7), 'ABE8.20': (4, 8), 'ABE8e': (4, 8), # SpABE8e matches CBE window (Richter 2020)
'evoCDA-BE': (1, 9),
}
window_lo, window_hi = window_by_editor[editor]
aa_index = target_aa - cds_protein_start # 0-indexed in protein
aa_start_nt = aa_index * 3 # nt offset in cds
candidates = []
spacer_len = 20
pam_pattern = re.compile(r'(?=([ACGT]GG))')
for strand, seq in [('+', cds_sequence), ('-', str(Seq(cds_sequence).reverse_complement()))]:
for pam_match in pam_pattern.finditer(seq):
pam_pos = pam_match.start()
spacer_start = pam_pos - spacer_len
if spacer_start < 0:
continue
spacer = seq[spacer_start:pam_pos]
# Editor-specific window from PAM-distal end (1-indexed)
# Find all editable bases in window
edit_bases_in_window = []
for i, b in enumerate(spacer[window_lo-1:window_hi], start=window_lo):
if b == target_base:
edit_bases_in_window.append(i)
if not edit_bases_in_window:
continue
# Annotate which edits hit the target_aa codon
target_codon_start = aa_start_nt
target_codon_end = target_codon_start + 3
target_position_in_spacer = []
for i in edit_bases_in_window:
genomic_pos = spacer_start + i - 1
if target_codon_start <= genomic_pos < target_codon_end:
target_position_in_spacer.append(i)
bystander_positions = [i for i in edit_bases_in_window if i not in target_position_in_spacer]
candidates.append({
'spacer': spacer,
'strand': strand,
'spacer_start': spacer_start,
'target_positions': target_position_in_spacer,
'bystander_positions': bystander_positions,
'n_bystanders': len(bystander_positions),
})
return pd.DataFrame(candidates).sort_values('n_bystanders')
```
**Decision rule:** Select spacers with target_positions != empty AND n_bystanders minimized. For variant-by-variant scanning, accept up to 1-2 bystanders if biology of those positions is interpretable; flag for downstream variant attribution.
## Editing Efficiency Filtering (Critical Pre-Hit-Calling)
**Goal:** Drop sgRNAs that do not edit efficiently, since unedited reads represent no biological perturbation.
**Approach:** From CRISPResso2 output, compute target-base-conversion percentage per sgRNA; filter library to sgRNAs with >50% target editing in a pilot or co-screened control.
```python
def filter_by_editing_efficiency(crispresso_outputs_dir, target_pos, target_base, efficiency_threshold=0.5):
'''Drop sgRNAs that edit <efficiency_threshold of reads at target position.
crispresso_outputs_dir: directory containing CRISPResso per-sample outputs.'''
from pathlib import Path
results = []
for sample_dir in Path(crispresso_outputs_dir).glob('CRISPResso_on_*'):
sgrna_id = sample_dir.name.replace('CRISPResso_on_', '')
quant_file = sample_dir / 'Quantification_window_nucleotide_percentage_table.txt'
if not quant_file.exists():
continue
df = pd.read_csv(quant_file, sep='\t')
# Find target position in the quantification window
target_row = df[df['Position'] == target_pos]
if target_row.empty:
continue
# Editing = sum of non-original bases at target position
original_pct = target_row[target_base].values[0]
editing_pct = (100 - original_pct) / 100
results.append({'sgrna_id': sgrna_id, 'editing_pct': editing_pct,
'pass_filter': editing_pct >= efficiency_threshold})
return pd.DataFrame(results)
```
**Convention:** Drop sgRNAs below 50% editing for variant-function screens. A common working split is a 30% editing floor for primary screening and a 50% floor for confirmed hits. Below 30%, the screen has insufficient power; above 70%, results approach saturation editing.
## Bystander Edit Attribution
**Why this matters:** When a sgRNA's editing window contains the target base AND a bystander base, the screen scores the combination. To attribute screen signal to the target variant alone, either (a) include sgRNAs that edit only the target (no bystander) -- often impossible -- or (b) deconvolute via parallel measurements.
**Strategies for variant-by-variant attribution:**
1. **Tile multiple sgRNAs with different bystander patterns:** If 5 different sgRNAs all hit the target base but have different bystanders, common signal across them is target-attributable (Hanna 2021 approach).
2. **Use orthogonal chemistry:** Run the same variant scan with prime editor (no bystanders); cross-validate. See [[prime-editing-screens]].
3. **Bystander stratification:** From CRISPResso2 allele table, partition reads by exact edit pattern (target only, target+bystander_1, target+bystander_2, etc.); separately score each pattern's contribution to the phenotype.
4. **Restrict library:** Use only sgRNAs with zero bystanders in the editing window (rare; may exclude most candidate spacers).
```python
def deconvolute_bystander(allele_table_path, target_pos, bystander_pos_list):
'''From CRISPResso2 allele table, partition reads by edit pattern at target + bystanders.
Returns: per-pattern frequency for each combination of target/bystander edits.'''
alleles = pd.read_csv(allele_table_path, sep='\t', compression='zip')
# Mark target_edited and per-bystander_edited
alleles['target_edited'] = alleles['Aligned_Sequence'].str[target_pos-1] != alleles['Reference_Sequence'].str[target_pos-1]
for bp in bystander_pos_list:
alleles[f'bystander_{bp}_edited'] = alleles['Aligned_Sequence'].str[bp-1] != alleles['Reference_Sequence'].str[bp-1]
return alleles.groupby(['target_edited'] + [f'bystander_{bp}_edited' for bp in bystander_pos_list])['Reference_pct'].sum().reset_index()
```
## Hit Calling for Variant-Function Screens
**Goal:** Score per-variant fitness from a base-editor screen.
**Approach:** Filter library to efficiency-passing sgRNAs (>50% editing), then run MAGeCK MLE or drugZ on the sgRNA-level counts; map each significant sgRNA to its predicted variant + bystander pattern; aggregate to per-variant scores.
```python
def aggregate_variant_scores(mageck_sgrna_summary, variant_annotation_df):
'''Aggregate sgRNA-level scores to per-variant scores.
variant_annotation_df: per-sgRNA -> predicted variants (target + bystanders).'''
df = mageck_sgrna_summary.merge(variant_annotation_df, on='sgRNA')
# Target-only contribution: sgRNAs with no bystanders
target_only = df[df['n_bystanders'] == 0]
target_only_scores = target_only.groupby('target_variant')['LFC'].agg(['mean', 'std', 'count'])
# Mixed signal: sgRNAs with bystanders
mixed = df[df['n_bystanders'] > 0]
return target_only_scores, mixed
```
## Hanna 2021 BRCA1/2 Variant-Function Screen Methodology
**Hanna et al 2021 *Cell* 184:1064** benchmarked CBE variant scanning at scale, screening 68,526 sgRNAs covering 52,034 ClinVar variants across 3,584 genes, with BRCA1 and BRCA2 as the positive/negative-selection benchmark:
1. Design the CBE library from predicted variant impact (ClinVar annotation), covering each variant with the sgRNAs that install it
2. Run drug-modifier screens (PARPi sensitivity) with vehicle vs drug
3. Score per variant by aggregating over all sgRNAs that install it; cross-check against bystander-controlled sgRNAs
**Standard surrounding practice:** verify editing efficiency at a control timepoint via amplicon sequencing, drop low-efficiency sgRNAs (see the editing-efficiency convention above), and call sensitizers with a bidirectional method such as drugZ.
**Quantified result:** Recovered known loss-of-function variants in BRCA1 and BRCA2 with high precision, and identified PARP1 variants conferring resistance to PARP inhibitors.
## Cuella-Martin 2021 DDR-Gene Variant Screening
**Cuella-Martin et al 2021 *Cell* 184:1081-1097** screened ~86 DNA-damage-response (DDR) genes (including BRCA1/2) with CBE saturation mutagenesis:
- Saturation CBE design across 86 DDR genes (not BRCA1/2 alone)
- Identified pathogenic/likely-pathogenic variants in critical protein domains
- Combined with biochemical and genetic validation (for example the 53BP1-USP28 interaction surface)
- Demonstrated saturation mutagenesis is feasible at protein-domain scale
**Relationship to Hanna 2021:** the two studies appeared back-to-back in the same *Cell* issue and apply the same CBE variant-scanning strategy to complementary targets -- Hanna benchmarks against ClinVar-annotated variants genome-wide, Cuella-Martin saturates 86 DDR genes. Treat them as complementary methodology references, not as cross-validations of each other.
## Cas9 vs Base Editor vs Prime Editor for Variant Installation
| Approach | What it does | Bystander | Indels | When to use |
|----------|--------------|-----------|--------|-------------|
| Cas9 + HDR template | Installs precise edit + template | None | High (NHEJ competition) | When precise edit needed; high indel byproduct |
| Cas9 (no template) | Random indels at cut site | None | 70%+ | Loss-of-function; not variant-specific |
| CBE (BE3/BE4) | C->T at editing window | Yes (multiple Cs) | <5% | C->T variants with manageable bystanders |
| ABE (ABE7.10/ABE8e) | A->G at editing window | Yes (multiple As) | <2% | A->G variants; clean for single-A spacers |
| CGBE / GBE | C->G or C->A | Yes | 5-10% | Transversions; rare use cases |
| Prime editor (PE2/PE3) | Templated edit; any base change | None | 1-3% | Precise variants; lower efficiency |
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